Hostname: page-component-8448b6f56d-cfpbc Total loading time: 0 Render date: 2024-04-18T06:32:32.663Z Has data issue: false hasContentIssue false
  • English
  • Français

Spontaneous aberrant right subclavian arterio-oesophageal fistula in a previously healthy child

Published online by Cambridge University Press:  12 December 2014

Michael R. Joynt  and
Ronald G. Grifka
Michael R. Joynt*
Affiliation:
Department of Pediatrics and Communicable Diseases, Division of Pediatric Cardiology, C.S. Mott Children’s Hospital, University of Michigan, Ann Arbor, Michigan, United States of America
Ronald G. Grifka
Affiliation:
Department of Pediatrics and Communicable Diseases, Division of Pediatric Cardiology, C.S. Mott Children’s Hospital, University of Michigan, Ann Arbor, Michigan, United States of America
*
Correspondence to: M. R. Joynt, University of Michigan, Department of Pediatrics and Communicable Diseases, Congenital Heart Center, Division of Pediatric Cardiology, C.S. Mott Children’s Hospital, University of Michigan. 1540 East Hospital Drive, Ann Arbor, MI, 48109-4202, United States of America. Tel: (734) 764-5177; Fax: (734) 936-9470; E-mail: mjoynt@med.umich.edu
Get access Rights & Permissions [Opens in a new window]

Abstract

An aberrant right subclavian artery arising from a left aortic arch is the most frequently described congenital aortic arch anomaly, occurring in 0.5 to 2.3% of the general population. Despite the retro-oesophageal course of the aberrant subclavian artery, an arterio-oesophageal fistula is an uncommon finding, only previously reported as a very rare complication in critically ill patients with oesophageal instrumentation or foreign body ingestion. We describe a unique case of a spontaneous aberrant right subclavian arterio-oesophageal fistula without an inciting event in a 17-month-child.

Keywords

Aberrant right subclavianarterio-oesophageal fistulaspontaneous fistula
Type
Brief Reports
Information
Cardiology in the Young , Volume 25 , Issue 7 , October 2015 , pp. 1425 - 1427
Check for updates
Copyright
© Cambridge University Press 2014 

Access options

Get access to the full version of this content by using one of the access options below. (Log in options will check for institutional or personal access. Content may require purchase if you do not have access.)

References

1. Molz, G, Burri, B. Aberrant subclavian artery (Arteria lusoria): sex differences in the prevalence of various forms of the malformation. Virchows Archiv A 1978; 380: 303–315.Google Scholar
2. Zapata, H, Edwards, J, Titus, J. Aberrant right subclavian artery with left aortic arch: associated cardiac anomalies. Pediatric Cardiology 1993; 14: 159–161.CrossRefGoogle ScholarPubMed
3. Ramos-Duran, L, et al. Developmental aortic arch anomalies in infants and children assessed with CT angiography. Am J Roentgenol 2012; 198: W466–W474.CrossRefGoogle ScholarPubMed
4. Miller, RG, et al. Survival after aberrant right subclavian artery-esophageal fistula: case report and literature review. J Vasc Surg 1996; 24: 271–275.Google Scholar
5. Epstein, DA, DeBord, JR. Abnormalities associated with aberrant right subclavian arteries: a case report. Vasc Endovasc Surg 2002; 36: 297–303.CrossRefGoogle ScholarPubMed
6. Weinburg, PM. Aortic Arch Anomalies: Moss and Adam’s Heart Disease in Infants, Children, and Adolescents: Including the Fetus and Young Adults, 7th edn. Vol. 1, Lippincott Williams & Wilkins, Philadelphia, PA, 2008.Google Scholar
7. Belkin, R, et al. Aberrant right subclavian artery-esophageal fistula: a cause of overwhelming upper gastrointestinal hemorrhage. Cardiovasc Interv Radiol 1984; 7: 87–89.CrossRefGoogle ScholarPubMed
8. Fuentes, S, et al. Arterial-esophageal fistula: a severe complication in children with cardiovascular abnormalities. Pediatr Surg Int 2010; 26: 335–337.Google Scholar
9. Millar, A, et al. Upper gastrointestinal bleeding secondary to an aberrant right subclavian artery-esophageal fistula: a case report and review of the literature. Can J Gastroenterol 2007; 21: 389–392.CrossRefGoogle Scholar
10. Hollander, JE, Quick, G. Aortoesophageal fistula: a comprehensive review of the literature. Am J Med 1991; 91: 279–287.Google Scholar